Psammomatoid juvenile ossifying fibroma (PJOF) is a rare uncommon, benign fibroosseous variant of ossifying fibroma. It usually affects paranasal sinuses, orbit & skull. Although a benign entity juvenile ossifying fibroma is known to be locally aggressive & has a high tendency to recur. To aim of this paper to report a case of extensive PJOF with Dentigerous cyst in which complete excision of tumour and cyst enucleation was done by intraoral surgical approach. A 7-year-old male patient presented with mass on left side of middle third of face since last 2 years. In Left side cheek he noticed fullness & experienced pressure with no other dental or ophthalmic symptoms. After clinical, radiological & histopathological examination the diagnosis was confirmed as PJOF with dentigerous cyst. Intraoral surgical approach was performed and complete excision of tumour and cyst enucleation was done under GA. Good cicatrisation soft he intraoral wound were evident. He was on follow-up since last 1year and no sign of recurrence or any complication.